GENERAL NEUROLOGY
One and a half syndrome
Updated on 21/08/2024, published on 21/08/2024
One and a half syndrome is a rare neurological disorder characterized by a unique combination of horizontal gaze palsy and internuclear ophthalmoplegia. This complex oculomotor disorder was first described by Fisher in 1967
Etiopathogenesis
Anatomic substrate of horizontal gaze
- a trio of brainstem structures working in perfect harmony are involved in horizontal gaze
- paramedian pontine reticular formation (PPRF), also known as horizontal gaze center, is located in the pons and initiates and controls horizontal saccades (under control of cortical centers)
- the abducens nucleus (CN VI) controls the lateral rectus muscle, which abducts the ipsilateral eye (moves it outward)
- medial longitudinal fasciculus (MLF) is a white matter tract that coordinates conjugate eye movements between both eyes (it connects the abducens nucleus with the contralateral oculomotor nucleus)
- the brainstem center is directed by the cortex
- frontal eye fields (FEF) is located in the frontal lobe and is involved in voluntary saccades and visual attention
- parietal eye fields (PEF) help with spatial orientation and reflexive saccades
- supplementary eye fields (SEF) contribute to the planning and execution of complex eye movement sequences
- the magic happens when all these structures communicate. Here’s a simplified breakdown of the main pathways:
- cortex → brainstem: signals from the FEF, PEF, and SEF travel to the PPRF, initiating horizontal eye movements
- PPRF → abducens nucleus: the PPRF activates the abducens nucleus, which stimulates the lateral rectus muscle of the ipsilateral eye
- PPRF → contralateral CN III: simultaneously, signals cross to the opposite side to activate the medial rectus muscle of the contralateral eye via the MLF
Pathophysiology
- isolated lesion in the MLF leads to internuclear ophthalmoplegia (INO)
- isolated damage to the PPRF results in the inability to generate horizontal eye movements (horizontal gaze palsy)
- one and a half syndrome results from a lesion in the PPRF and/or the abducens nucleus, combined with interruption of the internuclear fibers of the MLF
- most common causes:
- stroke (ischemic or hemorrhagic)
- multiple sclerosis
- brainstem tumors
- infections (e.g., tuberculosis, neurocysticercosis)
Clinical Presentation
- horizontal gaze palsy to the side of the lesion (one)
- internuclear ophthalmoplegia on attempted gaze to the opposite side
- the adducting eye (same side as the lesion) fails to move past the midline (half)
- the abducting eye (contralateral to the lesion) shows nystagmus
- vertical eye movements are preserved
- diplopia, oscillopsia, and balance problems may occur
Diagnostic evaluation
- detailed neurological examination focused on eye movements and other brainstem functions
- evaluate nystagmus and skew deviation, convergence, and vertical eye movements
- MRI (Magnetic Resonance Imaging) incl. DWI is the gold standard for the detection of lesions
- DTI (diffusion tensor imaging) evaluates white matter tract integrity, particularly of the MLF
Management
- treatment of the underlying cause (thrombolysis, surgery, radiotherapy, etc.)
- symptomatic therapy
- prism glasses to alleviate diplopia
- vestibular rehabilitation exercises
- occupational therapy to improve daily functioning